NEJM:妊娠性类天疱疮-病例报道

2020-08-27 MedSci原创 MedSci原创

妊娠性类天疱疮是一种罕见的自身免疫性皮肤病,其特征是起疱,通常表现在妊娠中后期。

患者为一名30岁孕妇,妊娠34周,因出现皮疹5天而到急诊科就诊。皮疹从腹部开始发病,并扩散到胸部、手臂和腿部。口腔和鼻腔粘膜、头部、颈部皮肤未受影响。

体格检查发现手臂(如图A所示)和腹部(如图B所示)有融合的丘疹和水泡。没有明显的淋巴结肿大。血液检查表明抗bulg的天疱疮180抗体水平高于每毫升200 U,这是检测上限(正常范围0至20)。接受抗核抗体,抗大疱性天疱疮180抗体超过230U/ml(正常范围为0~20)。血液中抗核抗体、抗大疱性天疱疮230抗体、抗纤维蛋白1、抗纤维蛋白3抗体均正常。皮肤活检标本显示轻微乳头间海绵状病,并延伸至皮肤附件,浅表血管周围有少量嗜酸性粒细胞浸润。免疫荧光检测到皮肤下基底膜中的IgM、IgG和C3,诊断为妊娠性类天疱疮(以前是疱疹妊娠)。

妊娠性类天疱疮是一种罕见的自身免疫性皮肤病,其特征是起疱,通常表现在妊娠中后期。

该患者接受全身性糖皮质激素治疗,皮疹在3个月内消失。妊娠38周时,她自发分娩。婴儿很健康,没有皮疹。

原始出处:

Paolo Agostinis,et al.Pemphigoid Gestationis.N Engl J Med 2020;https://www.nejm.org/doi/full/10.1056/NEJMicm2000922

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    2020-09-05 1070030296

    学习了,很特殊

    0

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    2020-08-28 ms6000001113694287

    学习了

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    2020-08-27 ms7000001791634956

    特殊病历

    0

  4. [GetPortalCommentsPageByObjectIdResponse(id=882974, encodeId=8a0f8829e4ad, content=学习了,很特殊, beContent=null, objectType=article, channel=null, level=null, likeNumber=98, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=http://cacheapi.medsci.cn/resource/upload/20161015/IMG5801C4A734E137989.jpg, createdBy=51871947992, createdName=1070030296, createdTime=Sat Sep 05 21:06:52 CST 2020, time=2020-09-05, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814750, encodeId=1155814e50e4, content=学习了, beContent=null, objectType=article, channel=null, level=null, likeNumber=129, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20200729/2ee0ca079ce64987b1195eb6aa20a1f4/ae923a98c9704879bacdc81d9fa7479a.jpg, createdBy=a3ab5398909, createdName=ms6000001113694287, createdTime=Fri Aug 28 16:39:52 CST 2020, time=2020-08-28, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814348, encodeId=390581434836, content=特殊病历, beContent=null, objectType=article, channel=null, level=null, likeNumber=0, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=c7125412073, createdName=ms7000001791634956, createdTime=Thu Aug 27 22:21:46 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814316, encodeId=7e4d814316e7, content=标记一下回头来看, beContent=null, objectType=article, channel=null, level=null, likeNumber=95, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=8ce05381686, createdName=ms4000002082197205, createdTime=Thu Aug 27 22:01:16 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814187, encodeId=ab2f81418eb5, content=好资料, beContent=null, objectType=article, channel=null, level=null, likeNumber=105, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=8ce05381686, createdName=ms4000002082197205, createdTime=Thu Aug 27 18:17:56 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814080, encodeId=882f81408000, content=密恐患者颤颤巍巍点进来…🤣, beContent=null, objectType=article, channel=null, level=null, likeNumber=36, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20210607/9f00a0de660e4b36b77a9a5f7620d6bf/98c22b17ddf7446fa7b9a618fabcb9f7.jpg, createdBy=a8fb2299762, createdName=Psycho.Dr Du, createdTime=Thu Aug 27 15:18:30 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814038, encodeId=b6f781403897, content=学习了, beContent=null, objectType=article, channel=null, level=null, likeNumber=21, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20200827/23619d3c1e944e23a9350a54edbacb81/d195c15802ae49df9886c39d3dcf868e.jpg, createdBy=e4295413629, createdName=ms3000000956234844, createdTime=Thu Aug 27 12:45:39 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814037, encodeId=af5481403e50, content=新手小白, beContent=null, objectType=article, channel=null, level=null, likeNumber=26, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=67ef5413639, createdName=兔豆, createdTime=Thu Aug 27 12:44:45 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814000, encodeId=1b86814000a4, content=学习了, beContent=null, objectType=article, channel=null, level=null, likeNumber=23, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20200827/23619d3c1e944e23a9350a54edbacb81/d195c15802ae49df9886c39d3dcf868e.jpg, createdBy=e4295413629, createdName=ms3000000956234844, createdTime=Thu Aug 27 12:00:24 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=1035391, encodeId=139f10353912f, content=顶刊就是顶刊,谢谢梅斯带来这么高水平的研究报道,我们科里同事经常看梅斯,分享梅斯上的信息, beContent=null, objectType=article, channel=null, level=null, likeNumber=30, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=f0620, createdName=旺医, createdTime=Thu Aug 27 11:42:49 CST 2020, time=2020-08-27, status=1, ipAttribution=)]
    2020-08-27 ms4000002082197205

    标记一下回头来看

    0

  5. [GetPortalCommentsPageByObjectIdResponse(id=882974, encodeId=8a0f8829e4ad, content=学习了,很特殊, beContent=null, objectType=article, channel=null, level=null, likeNumber=98, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=http://cacheapi.medsci.cn/resource/upload/20161015/IMG5801C4A734E137989.jpg, createdBy=51871947992, createdName=1070030296, createdTime=Sat Sep 05 21:06:52 CST 2020, time=2020-09-05, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814750, encodeId=1155814e50e4, content=学习了, beContent=null, objectType=article, channel=null, level=null, likeNumber=129, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20200729/2ee0ca079ce64987b1195eb6aa20a1f4/ae923a98c9704879bacdc81d9fa7479a.jpg, createdBy=a3ab5398909, createdName=ms6000001113694287, createdTime=Fri Aug 28 16:39:52 CST 2020, time=2020-08-28, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814348, encodeId=390581434836, content=特殊病历, beContent=null, objectType=article, channel=null, level=null, likeNumber=0, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=c7125412073, createdName=ms7000001791634956, createdTime=Thu Aug 27 22:21:46 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814316, encodeId=7e4d814316e7, content=标记一下回头来看, beContent=null, objectType=article, channel=null, level=null, likeNumber=95, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=8ce05381686, createdName=ms4000002082197205, createdTime=Thu Aug 27 22:01:16 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814187, encodeId=ab2f81418eb5, content=好资料, beContent=null, objectType=article, channel=null, level=null, likeNumber=105, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=8ce05381686, createdName=ms4000002082197205, createdTime=Thu Aug 27 18:17:56 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814080, encodeId=882f81408000, content=密恐患者颤颤巍巍点进来…🤣, beContent=null, objectType=article, channel=null, level=null, likeNumber=36, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20210607/9f00a0de660e4b36b77a9a5f7620d6bf/98c22b17ddf7446fa7b9a618fabcb9f7.jpg, createdBy=a8fb2299762, createdName=Psycho.Dr Du, createdTime=Thu Aug 27 15:18:30 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814038, encodeId=b6f781403897, content=学习了, beContent=null, objectType=article, channel=null, level=null, likeNumber=21, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20200827/23619d3c1e944e23a9350a54edbacb81/d195c15802ae49df9886c39d3dcf868e.jpg, createdBy=e4295413629, createdName=ms3000000956234844, createdTime=Thu Aug 27 12:45:39 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814037, encodeId=af5481403e50, content=新手小白, beContent=null, objectType=article, channel=null, level=null, likeNumber=26, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=67ef5413639, createdName=兔豆, createdTime=Thu Aug 27 12:44:45 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=814000, encodeId=1b86814000a4, content=学习了, beContent=null, objectType=article, channel=null, level=null, likeNumber=23, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=https://img.medsci.cn/20200827/23619d3c1e944e23a9350a54edbacb81/d195c15802ae49df9886c39d3dcf868e.jpg, createdBy=e4295413629, createdName=ms3000000956234844, createdTime=Thu Aug 27 12:00:24 CST 2020, time=2020-08-27, status=1, ipAttribution=), GetPortalCommentsPageByObjectIdResponse(id=1035391, encodeId=139f10353912f, content=顶刊就是顶刊,谢谢梅斯带来这么高水平的研究报道,我们科里同事经常看梅斯,分享梅斯上的信息, beContent=null, objectType=article, channel=null, level=null, likeNumber=30, replyNumber=0, topicName=null, topicId=null, topicList=[], attachment=null, authenticateStatus=null, createdAvatar=null, createdBy=f0620, createdName=旺医, createdTime=Thu Aug 27 11:42:49 CST 2020, time=2020-08-27, status=1, ipAttribution=)]
    2020-08-27 ms4000002082197205

    好资料

    0

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    2020-08-27 Psycho.Dr Du

    密恐患者颤颤巍巍点进来…🤣

    0

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    2020-08-27 ms3000000956234844

    学习了

    0

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    2020-08-27 兔豆

    新手小白

    0

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    2020-08-27 ms3000000956234844

    学习了

    0

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    2020-08-27 旺医

    顶刊就是顶刊,谢谢梅斯带来这么高水平的研究报道,我们科里同事经常看梅斯,分享梅斯上的信息

    0

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